Overview

Optic nerve hypoplasia is an under-development of the optic nerve resulting in a reduced number of axons in the involved nerve. It may be bilateral or, more rarely unilateral (15-25% of cases). Supporting tissues and retinal vasculature develop normally. It may occur with in conjunction with microphthalmos, aniridia, coloboma, nystagmus, strabismus, facial anomalies, cranial abnormalities or occur independently of all these.

This condition is associated with a reduction in visual acuity that may range from light perception through to slightly sub-normal vision. Clinically, a very small optic nerve head is seen often surrounded by a ring of sclera.

OCT shows a thinning of the retinal nerve fibre layer (RNFL) and ganglion cell layer. The absence of a normal retinal nerve fibre layer can also be appreciated subjectively on red-free imaging which shows reduced reflectivity of the RNFL.

Case Examples

Differential diagnosis

References

Chen C, Yin J, Lewis RA, et al (2017) Genetic causes of optic nerve hypoplasia Journal of Medical Genetics 2017;54:441-449.

Garcia-Filion, P., & Borchert, M. (2013). Optic nerve hypoplasia syndrome: a review of the epidemiology and clinical associations. Current treatment options in neurology, 15(1), 78–89. https://doi.org/10.1007/s11940-012-0209-2